Journal of Research in Dental
and Maxillofacial Sciences
Volume 10, Issue 4 (12-2025)
J Res Dent Maxillofac Sci 2025, 10(4): 346-352 |
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Sharifzadeh S S, Mardani M, Motazedian J, Jamalpour M, Shirvani Farsani F, Entezar-e-Ghaem M et al . An Exceptionally Rare Case of Craniofacial Teratoma in A 2-Day-Old Infant: A Case Report. J Res Dent Maxillofac Sci 2025; 10 (4) :346-352
URL: http://jrdms.dentaliau.ac.ir/article-1-1115-en.html
URL: http://jrdms.dentaliau.ac.ir/article-1-1115-en.html
Seyedeh saba Sharifzadeh1 
, Mohesen Mardani2 , Jamaledin Motazedian3 , Mahdi Jamalpour4 , Fatemeh Shirvani Farsani5 , Mahjoubeh Entezar-e-Ghaem6 , Niloofar Ghadimi *7
, Mohesen Mardani2 , Jamaledin Motazedian3 , Mahdi Jamalpour4 , Fatemeh Shirvani Farsani5 , Mahjoubeh Entezar-e-Ghaem6 , Niloofar Ghadimi *7
1- Department of Oral Medicine, TeMS.C., Islamic Azad University, Tehran, Iran
2- Department of Oral and Maxillofacial Surgery, School of Dentistry, Shiraz University of Medical Sciences, Shiraz, Iran
3- Department of Oral and Maxillofacial Surgery, Shiraz University of Medical Sciences, Shiraz, Iran
4- Department of Pathology, Shiraz University of Medical Sciences, Shiraz, Iran
5- Department of Oral and Maxillofacial Surgery, Faculty of Dentistry, Hamedan University of Medical Sciences, Hamedan, Iran
6- Department of Oral and Maxillofacial Radiology, School of Dentistry, Shahid Sadoughi, Yazd, Iran
7- Department of Oral and Maxillofacial Radiology, Medical Dental Material Research Center. Dental School, TeMS.C., Islamic Azad University, Tehran, Iran ,omfrghadimi@gmail.com
2- Department of Oral and Maxillofacial Surgery, School of Dentistry, Shiraz University of Medical Sciences, Shiraz, Iran
3- Department of Oral and Maxillofacial Surgery, Shiraz University of Medical Sciences, Shiraz, Iran
4- Department of Pathology, Shiraz University of Medical Sciences, Shiraz, Iran
5- Department of Oral and Maxillofacial Surgery, Faculty of Dentistry, Hamedan University of Medical Sciences, Hamedan, Iran
6- Department of Oral and Maxillofacial Radiology, School of Dentistry, Shahid Sadoughi, Yazd, Iran
7- Department of Oral and Maxillofacial Radiology, Medical Dental Material Research Center. Dental School, TeMS.C., Islamic Azad University, Tehran, Iran ,
Abstract: (259 Views)
Background and Aim: Craniofacial teratomas are exceedingly rare congenital tumors, typically presenting at birth with variable degrees of facial distortion and airway compromise.
Case Presentation: We report a rare case of a 2-day-old female neonate with a massive craniofacial teratoma affecting her left facial region, accompanied by a cleft palate and feeding difficulties. Computed tomography (CT) imaging revealed a large heterogeneous mass with destructive extension into the orbit, maxilla, mandible, and anterior and middle cranial fossae. Complete surgical excision was achieved via the Weber-Ferguson approach, and histopathological evaluation confirmed a mature teratoma.
Conclusion: This case report highlights the importance of early imaging and prompt surgical intervention in managing large craniofacial teratomas. Despite the rarity of such cases, multidisciplinary planning is essential to achieve optimal functional and cosmetic outcomes.
Case Presentation: We report a rare case of a 2-day-old female neonate with a massive craniofacial teratoma affecting her left facial region, accompanied by a cleft palate and feeding difficulties. Computed tomography (CT) imaging revealed a large heterogeneous mass with destructive extension into the orbit, maxilla, mandible, and anterior and middle cranial fossae. Complete surgical excision was achieved via the Weber-Ferguson approach, and histopathological evaluation confirmed a mature teratoma.
Conclusion: This case report highlights the importance of early imaging and prompt surgical intervention in managing large craniofacial teratomas. Despite the rarity of such cases, multidisciplinary planning is essential to achieve optimal functional and cosmetic outcomes.
Type of Study: Case report |
Subject:
Oral & maxillofacial surgery
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